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Complementary to mammalian models, zebrafish has emerged as an interesting species to evaluate chemical treatments against these human skeletal disorders. Due to its versatility and the low cost of experiments, more than 80 models are currently available. In this article, we review the state-of-art of this \u201caquarium to bedside\u201d approach describing the models according to the list provided by the Nosology Committee. With this, we intend to stimulate research in the appropriate direction to efficiently meet the actual needs of clinicians under the scope of the Nosology Committee.<\/jats:p>","DOI":"10.3389\/fgene.2021.675331","type":"journal-article","created":{"date-parts":[[2021,8,5]],"date-time":"2021-08-05T08:38:04Z","timestamp":1628152684000},"update-policy":"https:\/\/doi.org\/10.3389\/crossmark-policy","source":"Crossref","is-referenced-by-count":29,"title":["Zebrafish Models for Human Skeletal Disorders"],"prefix":"10.3389","volume":"12","author":[{"given":"Manuel","family":"Mar\u00ed-Beffa","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ana B.","family":"Mesa-Rom\u00e1n","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ivan","family":"Duran","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"1965","published-online":{"date-parts":[[2021,8,5]]},"reference":[{"key":"B1","doi-asserted-by":"crossref","first-page":"1272","DOI":"10.1093\/hmg\/ddr557","article-title":"A meckelin\u2013filamin A interaction mediates ciliogenesis.","volume":"21","author":"Adams","year":"2012","journal-title":"Hum. 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