{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,8]],"date-time":"2026-05-08T17:15:21Z","timestamp":1778260521239,"version":"3.51.4"},"reference-count":15,"publisher":"Frontiers Media SA","license":[{"start":{"date-parts":[[2021,9,15]],"date-time":"2021-09-15T00:00:00Z","timestamp":1631664000000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["frontiersin.org"],"crossmark-restriction":true},"short-container-title":["Front. Pediatr."],"abstract":"<jats:p><jats:bold>Background:<\/jats:bold> Bronchial Dieulafoy's disease (BDD), characterized by constant diameter arterial malformation, is rare, especially among infants. The pathogenesis and clinical features of pediatric patients are unknown. Misdiagnosis and biopsy operations may lead to potential massive hemorrhage, which endangers the patient's life.<\/jats:p><jats:p><jats:bold>Case Presentation:<\/jats:bold> Here, we present a case of a 9-month-old boy who was diagnosed with BDD with massive hemoptysis. The boy was cured by embolization of the bronchial artery and was in good health at the 1-year follow-up. In addition, we searched PubMed, Google Scholar, and Web of Science databases using keyword \u201cBronchial Dieulafoy's Disease (BDD)\u201d and found six additional cases of pediatric BDD.<\/jats:p><jats:p><jats:bold>Conclusion:<\/jats:bold> It is still insufficient to draw a conclusion about the origin of the disease. Bronchial angiography and endobronchial ultrasonography are considered promising methods to diagnose Dieulafoy's disease of the bronchus. Bronchoscopy with transbronchial biopsy should not be deployed due to the high risk of fatal hemorrhage. Explicit clinical case reports of BDD are needed to enhance the understanding of this rare disease.<\/jats:p>","DOI":"10.3389\/fped.2021.674509","type":"journal-article","created":{"date-parts":[[2021,9,15]],"date-time":"2021-09-15T13:33:44Z","timestamp":1631712824000},"update-policy":"https:\/\/doi.org\/10.3389\/crossmark-policy","source":"Crossref","is-referenced-by-count":9,"title":["Case Report: A Case of Infant Bronchial Dieulafoy's Disease and Article Review"],"prefix":"10.3389","volume":"9","author":[{"given":"Yang","family":"Chen","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Yiting","family":"Mao","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Xingfeng","family":"Cheng","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ruihua","family":"Xiong","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ying","family":"Lan","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Feng","family":"Chen","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Furong","family":"Zhang","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Jun","family":"Liu","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Yanting","family":"Wu","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"1965","published-online":{"date-parts":[[2021,9,15]]},"reference":[{"key":"B1","author":"Dieulafoy","year":"1900","journal-title":"Clinique M\u00e9dicale de l'Hotel-Dieu de Paris"},{"key":"B2","doi-asserted-by":"publisher","first-page":"697","DOI":"10.1136\/thx.50.6.697","article-title":"Dieulafoy's disease of the bronchus","volume":"50","author":"Sweerts","year":"1995","journal-title":"Thorax."},{"key":"B3","doi-asserted-by":"publisher","first-page":"58","DOI":"10.1186\/1465-9921-9-58","article-title":"Approach to diagnosis and pathological examination in bronchial dieulafoy disease: a case series","volume":"9","author":"Parrot","year":"2008","journal-title":"Respir Res."},{"key":"B4","doi-asserted-by":"publisher","first-page":"20","DOI":"10.1016\/j.rmcr.2015.04.007","article-title":"Endobronchial ultrasound and bronchial artery embolization for dieulafoy's disease of the bronchus in a teenager: a case report","volume":"16","author":"Ganganah","year":"2015","journal-title":"Respir Med Case Rep."},{"key":"B5","doi-asserted-by":"publisher","first-page":"191","DOI":"10.1186\/s13019-014-0191-8","article-title":"Dieulafoy's disease of the bronchus: report of a case and review of the literature","volume":"9","author":"Fang","year":"2014","journal-title":"J Cardiothorac Surg."},{"key":"B6","doi-asserted-by":"publisher","first-page":"244","DOI":"10.4103\/atm.ATM_163_20","article-title":"A rare cause of massive hemoptysis in a child: bronchial dieulafoy's disease - the first report of transcatheter treatment in pediatric age","volume":"15","author":"Giordano","year":"2020","journal-title":"Ann Thorac Med."},{"key":"B7","doi-asserted-by":"publisher","first-page":"100","DOI":"10.1016\/j.prrv.2020.06.001","article-title":"Massive paediatric pulmonary haemorrhage in dieulafoy's disease: roles of CT angiography, embolisation and bronchoscopy","volume":"36","author":"Woodhull","year":"2020","journal-title":"Paediatr Respir Rev."},{"key":"B8","doi-asserted-by":"publisher","first-page":"273","DOI":"10.3389\/fped.2020.00273","article-title":"Bronchial dieulafoy's disease in children: a case report and review of literature","volume":"8","author":"Yeh","year":"2020","journal-title":"Front Pediatr."},{"key":"B9","doi-asserted-by":"publisher","first-page":"731","DOI":"10.3760\/cma.j.issn.0529-5807.2017.10.017","article-title":"[Infantile dieulafoy's disease of bronchus: repor\/t of a case\/\/]","volume":"46","author":"Niu","year":"2017","journal-title":"Zhonghua Bing Li Xue Za Zhi."},{"key":"B10","doi-asserted-by":"publisher","first-page":"104","DOI":"10.1186\/s12890-019-0863-1","article-title":"Bronchial dieulafoy's disease: a retrospective analysis of 73 cases","volume":"19","author":"Qian","year":"2019","journal-title":"BMC Pulm Med."},{"key":"B11","doi-asserted-by":"publisher","first-page":"954","DOI":"10.1164\/rccm.201711-2184IM","article-title":"Bronchial dieulafoy's disease: visualization of embolization particles in bronchial aspirate","volume":"198","author":"Bonnefoy","year":"2018","journal-title":"Am J Respir Crit Care Med."},{"key":"B12","doi-asserted-by":"publisher","first-page":"166","DOI":"10.4081\/monaldi.2010.287","article-title":"Endobronchial ultrasound in dieulafoy's disease of the bronchus: an additional application of EBUS","volume":"73","author":"Gurioli","year":"2010","journal-title":"Monaldi Arch Chest Dis."},{"key":"B13","doi-asserted-by":"publisher","first-page":"148","DOI":"10.3760\/cma.j.issn.1001-0939.2015.02.026","article-title":"A case of bronchial artery-pulmonary artery fistula diagnosed by narrow-band imaging combined with bronchial arteriography","volume":"38","author":"Ting","year":"2015","journal-title":"Chinese J Tuberculosis Respir Dis."},{"key":"B14","doi-asserted-by":"publisher","first-page":"577","DOI":"10.3760\/cma.j.issn.1001-0939.2013.08.005","article-title":"[Dieulafoy disease of the bronchus: 3 cases report with literature review]","volume":"36","author":"Yang","year":"2013","journal-title":"Chinese J Tuberculosis Respir Dis."},{"key":"B15","doi-asserted-by":"publisher","first-page":"e14471","DOI":"10.1097\/MD.0000000000014471","article-title":"A case report and review of literature of dieulafoy's disease of bronchus: a rare life-threatening pathologic vascular condition","volume":"98","author":"Zhou","year":"2019","journal-title":"Medicine."}],"container-title":["Frontiers in Pediatrics"],"original-title":[],"link":[{"URL":"https:\/\/www.frontiersin.org\/articles\/10.3389\/fped.2021.674509\/full","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2021,9,15]],"date-time":"2021-09-15T13:33:51Z","timestamp":1631712831000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.frontiersin.org\/articles\/10.3389\/fped.2021.674509\/full"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2021,9,15]]},"references-count":15,"alternative-id":["10.3389\/fped.2021.674509"],"URL":"https:\/\/doi.org\/10.3389\/fped.2021.674509","relation":{},"ISSN":["2296-2360"],"issn-type":[{"value":"2296-2360","type":"electronic"}],"subject":[],"published":{"date-parts":[[2021,9,15]]},"article-number":"674509"}}