{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,14]],"date-time":"2026-09-14T22:49:11Z","timestamp":1789426151739,"version":"build-2803163510"},"reference-count":40,"publisher":"Frontiers Media SA","license":[{"start":{"date-parts":[[2022,9,22]],"date-time":"2022-09-22T00:00:00Z","timestamp":1663804800000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["frontiersin.org"],"crossmark-restriction":true},"short-container-title":["Front. Surg."],"abstract":"<jats:p>Cavernous lymphangioma often occurs in the head, neck, trunk, and extremities of infants and children, and it is rare to cause a small intestine intussusception in adults. In this case, a 32-year-old woman presented with abdominal pain, vomiting, and a 5\u2005cm\u2009\u00d7\u20095\u2005cm abdominal mass on the left side of the abdomen. Laboratory tests showed anemia and CT showed small intestinal intussusception. After conservative treatments, her symptoms disappeared. However, 18F-FDG PET\/CT suggested malignancy and her symptoms reappeared after eating something. Segmental jejunal resection was performed and pathology showed submucosal cavernous lymphangioma. At the 1-year follow-up, the patient was asymptomatic. Then this paper reviewed the literature on small intestinal cavernous lymphangioma in adults and found that this is the first English case report of intussusception caused by a jejunal submucosal cavernous lymphangioma in an adult. Current problem is that adult intussusception and intestinal lymphangioma are difficult to diagnose preoperatively. Imaging techniques such as tomography and PET\/CT aid in the diagnosis of these benign lesions. Surgical resection was considered to be the required treatment and seems to have had no recurrence in adults according to the literature.<\/jats:p>","DOI":"10.3389\/fsurg.2022.953840","type":"journal-article","created":{"date-parts":[[2022,9,22]],"date-time":"2022-09-22T00:27:53Z","timestamp":1663806473000},"update-policy":"https:\/\/doi.org\/10.3389\/crossmark-policy","source":"Crossref","is-referenced-by-count":7,"title":["Case report: Submucosal cavernous lymphangioma causing jejuno-jejunal intussusception in an adult"],"prefix":"10.3389","volume":"9","author":[{"given":"Ning","family":"Zhao","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Yuhang","family":"Fu","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Zhongzheng","family":"Wang","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Qi","family":"An","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Wenzhuo","family":"Jia","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"1965","published-online":{"date-parts":[[2022,9,22]]},"reference":[{"key":"B1","doi-asserted-by":"publisher","first-page":"407","DOI":"10.3748\/wjg.15.407","article-title":"Intussusception of the bowel in adults: a review","volume":"15","author":"Marinis","year":"2009","journal-title":"World J Gastroenterol"},{"key":"B2","doi-asserted-by":"publisher","first-page":"134","DOI":"10.1007\/s00268-014-2759-9","article-title":"Adult intussusception: a retrospective review","volume":"39","author":"Honjo","year":"2015","journal-title":"World J Surg"},{"key":"B3","doi-asserted-by":"publisher","first-page":"795","DOI":"10.1016\/j.otohns.2010.02.026","article-title":"Lymphatic malformations: review of current treatment","volume":"142","author":"Perkins","year":"2010","journal-title":"Otolaryngol Head Neck Surg"},{"key":"B4","doi-asserted-by":"publisher","first-page":"62","DOI":"10.1111\/j.1440-1681.1985.tb00893.x","article-title":"Congenital malformations of the lymphatic system","volume":"3","author":"Fonkalsrud","year":"1994","journal-title":"Semin Pediatr Surg"},{"key":"B5","doi-asserted-by":"publisher","first-page":"363","DOI":"10.1007\/BF00308747","article-title":"Lymphangioma in the small intestine: report of a case and review of the Japanese literature","volume":"22","author":"Hanagiri","year":"1992","journal-title":"Surg Today"},{"key":"B6","doi-asserted-by":"publisher","first-page":"187","DOI":"10.1111\/j.1440-1673.1995.tb00270.x","article-title":"Retroperitoneal lymphangioma","volume":"39","author":"Breidahl","year":"1995","journal-title":"Australas Radiol"},{"key":"B7","doi-asserted-by":"publisher","first-page":"111","DOI":"10.15388\/LietChirur.2015.2.8250","article-title":"Abdominal lymphangiomas in adults: case report and literature review","volume":"14","author":"\u0160ileikis","year":"2015","journal-title":"Lietuvos Chirurgija"},{"key":"B8","doi-asserted-by":"publisher","first-page":"157","DOI":"10.1097\/00000658-196101000-00019","article-title":"Mesenteric cavernous lymphangiomata: brief review and report of two cases","volume":"153","author":"Viar","year":"1961","journal-title":"Ann Surg"},{"key":"B9","doi-asserted-by":"publisher","first-page":"2","DOI":"10.1136\/bcr.03.2011.4022","article-title":"Jejunal cavernous lymphangioma","volume":"2011","author":"Morris-Stiff","year":"2011","journal-title":"BMJ Case Rep"},{"key":"B10","doi-asserted-by":"publisher","first-page":"22","DOI":"10.1016\/j.ehpc.2017.12.003","article-title":"Jejunal lymphangioma and recurrent intussusception in an adult patient; 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