{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,4,7]],"date-time":"2026-04-07T22:44:34Z","timestamp":1775601874287,"version":"3.50.1"},"reference-count":23,"publisher":"MDPI AG","issue":"5","license":[{"start":{"date-parts":[[2022,5,16]],"date-time":"2022-05-16T00:00:00Z","timestamp":1652659200000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Children"],"abstract":"<jats:p>Objective: The North Star Ambulatory Assessment (NSAA) is a validated 17-item functional rating scale and widely used to assess motor function in boys with Duchenne muscular dystrophy (DMD). The SARS-CoV-2 pandemic and subsequent Government \u2018lockdown\u2019 resulted in no face-to-face clinic visits hence the motor abilities were not monitored. The aim was to investigate whether the NSAA was feasible and reliable by video assessment. Method: Ten ambulant DMD boys were selected from the electronic hospital records. Two physiotherapists scored the boys\u2019 NSAA independently and the intraclass correlation coefficient was used to assess agreement. The video scores were compared to two previous NSAA in-clinic scores. Results: Mean scores (SD) for clinic visit one were 22.6 (4.19) and clinic visit two 21.8 (5.3). The two physiotherapists video mean scores were 20.6 (5.66) for physiotherapist 1 and 20.6 (6.53) for physiotherapist 2. The intraclass correlation coefficient was 0.98 (95% CI 0.93\u20131.00) for the total NSAA and 1.00 (95% CI 1.00 to 1.00) for the rise time. The mean decline in score from clinic visit one (\u221212 months) to video assessment was 2.0 (2.8SD). Conclusion: The results from the study suggest that video NSAA is partially feasible and reliable.<\/jats:p>","DOI":"10.3390\/children9050728","type":"journal-article","created":{"date-parts":[[2022,5,16]],"date-time":"2022-05-16T13:06:23Z","timestamp":1652706383000},"page":"728","update-policy":"https:\/\/doi.org\/10.3390\/mdpi_crossmark_policy","source":"Crossref","is-referenced-by-count":5,"title":["Evaluating the Feasibility and Reliability of Remotely Delivering and Scoring the North Star Ambulatory Assessment in Ambulant Patients with Duchenne Muscular Dystrophy"],"prefix":"10.3390","volume":"9","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-9606-0574","authenticated-orcid":false,"given":"Nicholas","family":"Emery","sequence":"first","affiliation":[{"name":"Neuromuscular Service, TORCH Building, Robert Jones and Agnes Hunt Orthopaedic Hopsital, Shropshire SY10 7AG, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kate","family":"Strachan","sequence":"additional","affiliation":[{"name":"Neuromuscular Service, TORCH Building, Robert Jones and Agnes Hunt Orthopaedic Hopsital, Shropshire SY10 7AG, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-1613-1462","authenticated-orcid":false,"given":"Richa","family":"Kulshrestha","sequence":"additional","affiliation":[{"name":"Neuromuscular Service, TORCH Building, Robert Jones and Agnes Hunt Orthopaedic Hopsital, Shropshire SY10 7AG, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-7023-4078","authenticated-orcid":false,"given":"Jan Herman","family":"Kuiper","sequence":"additional","affiliation":[{"name":"Neuromuscular Service, TORCH Building, Robert Jones and Agnes Hunt Orthopaedic Hopsital, Shropshire SY10 7AG, UK"},{"name":"School of Pharmacy and Bioengineering, Keele University, Staffordshire ST5 5BG, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Tracey","family":"Willis","sequence":"additional","affiliation":[{"name":"Neuromuscular Service, TORCH Building, Robert Jones and Agnes Hunt Orthopaedic Hopsital, Shropshire SY10 7AG, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"1968","published-online":{"date-parts":[[2022,5,16]]},"reference":[{"key":"ref_1","doi-asserted-by":"crossref","first-page":"21","DOI":"10.1002\/mus.23810","article-title":"Report of MDA muscle disease symposium on newborn screening for Duchenne muscular dystrophy","volume":"48","author":"Mendell","year":"2013","journal-title":"Muscle Nerve"},{"key":"ref_2","doi-asserted-by":"crossref","first-page":"1049","DOI":"10.1038\/ejhg.2012.301","article-title":"Newborn bloodspot screening for Duchenne Muscular Dystrophy: 21 years-experience in Wales (UK)","volume":"21","author":"Moat","year":"2013","journal-title":"Eur. 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