{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,13]],"date-time":"2026-08-13T20:41:56Z","timestamp":1786653716931,"version":"build-2736575974"},"reference-count":12,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"6","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2014,6]]},"abstract":"<jats:p>A 70-year-old female patient presented with proptosis of right eye for the past 15 days and defective vision in both eyes since birth. She was found to have eccentric painful proptosis of right eye along with features of oculocutaneous albinism. Eccentric proptosis was due to an orbital mass which proved to be a plexiform neurofibroma by histopathological examination. The case is presented for its rarity, as an isolated orbital plexiform neurofibroma without the systemic features of neurofibromatosis is rare and its coincidental presentation with oculocutaneous albinism is yet rare and has not been reported so far.<\/jats:p>","DOI":"10.4103\/0301-4738.136259","type":"journal-article","created":{"date-parts":[[2014,7,8]],"date-time":"2014-07-08T00:48:23Z","timestamp":1404780503000},"page":"735-737","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":1,"title":["An unusual combination of Unilateral Orbital Plexiform Neurofibroma in a patient with oculocutaneous albinism"],"prefix":"10.4103","volume":"62","author":[{"given":"J","family":"Saravanan","sequence":"first","affiliation":[{"name":"Department of Ophthalmology, Coimbatore Medical College, Coimbatore, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"A","family":"Rajendraprasad","sequence":"additional","affiliation":[{"name":"Department of Ophthalmology, Coimbatore Medical College, Coimbatore, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"S","family":"Priyadharshni","sequence":"additional","affiliation":[{"name":"Department of Ophthalmology, Coimbatore Medical College, Coimbatore, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","reference":[{"key":"R1-20251008","doi-asserted-by":"crossref","first-page":"116","DOI":"10.1111\/j.1365-4632.2005.02386.x","article-title":"Clinicopathological study of neurofibromatosis type 1: An experience in Nigeria","volume":"44","author":"Odebode","year":"2005","journal-title":"Int J Dermatol"},{"key":"R2-20251008","doi-asserted-by":"crossref","first-page":"87","DOI":"10.1097\/00004397-198202210-00008","article-title":"Orbital tumors among Chinese in the Shanghai area","volume":"22","author":"Kuo","year":"1982","journal-title":"Int Ophthalmol Clin"},{"key":"R3-20251008","doi-asserted-by":"crossref","first-page":"319","DOI":"10.1097\/00004397-196206000-00004","article-title":"Orbital tumours in children: A report on 214 cases","volume":"2","author":"Porterfield","year":"1962","journal-title":"Int Ophthalmol Clin"},{"key":"R4-20251008","first-page":"1281","article-title":"Isolated orbital neurofibroma in NF-1 negative patients","volume":"94","author":"Funarunart","year":"2011","journal-title":"J Med Assoc Thai"},{"key":"R5-20251008","doi-asserted-by":"crossref","first-page":"47","DOI":"10.1007\/BF00346610","article-title":"Cerebro-vasculopathy and malignancy: Catastrophic complications of radiotherapy for optic nerve glioma in a von Recklinghausen neurofibromatosis patient","volume":"19","author":"Jamjoom","year":"1996","journal-title":"Neurosurg Rev"},{"key":"R6-20251008","first-page":"221","author":"Henderson","year":"1994","journal-title":"Orbital tumors"},{"key":"R8-20251008","doi-asserted-by":"crossref","first-page":"458","DOI":"10.1016\/0002-9394(85)90514-8","article-title":"Localized orbital neurofibromas","volume":"100","author":"Krohel","year":"1985","journal-title":"Am J Ophthalmol"},{"key":"R9-20251008","doi-asserted-by":"crossref","first-page":"485","DOI":"10.1136\/jmg.38.7.485","article-title":"A clinical study of patients with multiple isolated neurofibromas","volume":"38","author":"Blakley","year":"2001","journal-title":"J Med Genet"},{"key":"R10-20251008","doi-asserted-by":"crossref","first-page":"240","DOI":"10.1259\/dmfr\/83834938","article-title":"Intraorbital plexiform neurofibroma in an NF-1-negative patient","volume":"36","author":"Jank","year":"2007","journal-title":"Dentomaxillofacial Radiol"},{"key":"R11-20251008","first-page":"6","article-title":"A review of Oculocutaneous Albinism and its syndromes","volume":"2","author":"Olasode","year":"2006","journal-title":"Egypt Dermatol Online J"},{"key":"R12-20251008","doi-asserted-by":"crossref","first-page":"111","DOI":"10.18295\/2075-0528.1168","article-title":"Oculocutaneous Albinism associated with Axenfeld's Anomaly Three case reports","volume":"10","author":"Keshav","year":"2010","journal-title":"Sultan Qaboos Univ Med J"},{"key":"R13-20251008","doi-asserted-by":"crossref","first-page":"521","DOI":"10.1093\/brain\/97.1.521","article-title":"The familial association of neurofibromatosis, peroneal muscular atrophy, congenital deafness, partial albinism, and axenfeld's defect","volume":"97","author":"Bradley","year":"1974","journal-title":"Brain"}],"container-title":["Indian Journal of Ophthalmology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/02223307-201462060-00022","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,13]],"date-time":"2026-08-13T19:41:18Z","timestamp":1786650078000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/02223307-201462060-00022"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2014,6]]},"references-count":12,"journal-issue":{"issue":"6","published-print":{"date-parts":[[2014]]}},"URL":"https:\/\/doi.org\/10.4103\/0301-4738.136259","relation":{},"ISSN":["0301-4738","1998-3689"],"issn-type":[{"value":"0301-4738","type":"print"},{"value":"1998-3689","type":"electronic"}],"subject":[],"published":{"date-parts":[[2014,6]]},"assertion":[{"value":"2013-09-21","name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2013-12-19","name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}}]}}