{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,14]],"date-time":"2026-09-14T13:09:29Z","timestamp":1789391369457,"version":"build-2803163510"},"reference-count":6,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"1","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2024,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Rationale:<\/jats:title>\n                    <jats:p>This case report presents a rare combination of congenital anomalies in an otherwise healthy male infant born at 36 weeks. The infant was diagnosed with congenital maxillomandibular synechia, ectrodactyly, and ankyloglossia superior syndrome (ASS).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Patient Concerns:<\/jats:title>\n                    <jats:p>Inability to open the mouth completely, feeding challenges, and a cleft palate. The infant was stabilized through successful positive pressure ventilation via a face mask at birth and enteral feeding was initiated via a feeding gastrostomy.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Examination:<\/jats:title>\n                    <jats:p>Diagnostic tests revealed a midline palatal cleft, hypoplastic jaws, persistent metopic suture, and a bony fusion at the midline.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Treatment:<\/jats:title>\n                    <jats:p>Sectioning of the bony spur along the midline and achieving a mouth opening of 2 cm post-manipulation. The patient is under follow-up, with future treatment plans including cleft palate correction at 12 months and potential frontomandibular and lower jaw advancement depending on growth trajectories.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Take-away Lessons:<\/jats:title>\n                    <jats:p>This case underscores the complexity of managing multiple congenital anomalies and the need for individualized treatment plans.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.4103\/ijdr.ijdr_961_23","type":"journal-article","created":{"date-parts":[[2024,6,22]],"date-time":"2024-06-22T08:01:31Z","timestamp":1719043291000},"page":"117-119","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Maxillomandibular Fusion Along with Fusion of Dorsal Surface of the Tongue to the Hard Palate\u2014A Case Report"],"prefix":"10.4103","volume":"35","author":[{"given":"S. M.","family":"Balaji","sequence":"first","affiliation":[{"name":"Department of Oral and Maxillofacial Surgery, Balaji Dental and Craniofacial Hospital, Chennai, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Krishna","family":"Munnee","sequence":"additional","affiliation":[{"name":"Department of Plastic Surgery, Victoria Hospital, Mauritius"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Preetha","family":"Balaji","sequence":"additional","affiliation":[{"name":"Department of Oral and Maxillofacial Surgery, Balaji Dental and Craniofacial Hospital, Chennai, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Chris Joseph","family":"Chellaraj","sequence":"additional","affiliation":[{"name":"Department of Radiology, Tagore Medical College and Hospital, Chennai, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sachin","family":"Nishanth","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic, Balaji Dental and Craniofacial Hospital, Chennai, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Varsha Christy Rani","family":"Balaji","sequence":"additional","affiliation":[{"name":"Department of Obstetrics and Gynecology, Balaji Dental and Craniofacial Hospital, Chennai, Tamil Nadu, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2024,6,20]]},"reference":[{"key":"R1-20260914","doi-asserted-by":"crossref","first-page":"19","DOI":"10.1007\/s12663-019-01308-8","article-title":"Congenital maxillomandibular syngnathia: Review of literature and proposed new classification system","volume":"20","author":"Kumar","year":"2021","journal-title":"J Maxillofac Oral Surg"},{"key":"R2-20260914","doi-asserted-by":"crossref","first-page":"505","DOI":"10.1016\/j.ijom.2019.09.013","article-title":"Congenital syngnathia: Review of clinical profile and proposal of a new classification-based management protocol","volume":"49","author":"Olusanya","year":"2020","journal-title":"Int J Oral Maxillofac Surg"},{"key":"R3-20260914","doi-asserted-by":"crossref","first-page":"168","DOI":"10.4103\/2249-4863.184656","article-title":"Split-hand\/feet malformation: A rare syndrome","volume":"5","author":"Gane","year":"2016","journal-title":"J Family Med Prim Care"},{"key":"R4-20260914","doi-asserted-by":"crossref","first-page":"e35","DOI":"10.1055\/a-2070-8590","article-title":"Congenital Maxillomandibular synechia with multiple malformations in a very-low-birth-weight infant: A case report","volume":"13","author":"Uchi","year":"2023","journal-title":"Am J Perinatol Rep"},{"key":"R5-20260914","doi-asserted-by":"crossref","first-page":"170","DOI":"10.1016\/j.ydbio.2014.04.013","article-title":"Directed Bmp4 expression in neural crest cells generates a genetic model for the rare human bony syngnathia birth defect","volume":"391","author":"He","year":"2014","journal-title":"Dev Biol"},{"key":"R6-20260914","doi-asserted-by":"crossref","first-page":"906","DOI":"10.1177\/1055665620964028","article-title":"Ankyloglossia superior syndrome with complex craniofacial anomalies: Case report and literature review","volume":"58","author":"Hara","year":"2021","journal-title":"Cleft Palate Craniofac J"}],"container-title":["Indian Journal of Dental Research"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.4103\/ijdr.ijdr_961_23","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,9,14]],"date-time":"2026-09-14T13:00:29Z","timestamp":1789390829000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.4103\/ijdr.ijdr_961_23"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2024,1]]},"references-count":6,"journal-issue":{"issue":"1","published-print":{"date-parts":[[2024]]}},"URL":"https:\/\/doi.org\/10.4103\/ijdr.ijdr_961_23","relation":{},"ISSN":["0970-9290","1998-3603"],"issn-type":[{"value":"0970-9290","type":"print"},{"value":"1998-3603","type":"electronic"}],"subject":[],"published":{"date-parts":[[2024,1]]},"assertion":[{"value":"2023-11-28","name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2024-01-31","name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}}]}}