{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,10,16]],"date-time":"2026-10-16T03:00:48Z","timestamp":1792119648432,"version":"4.4.0"},"reference-count":6,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","license":[{"start":{"date-parts":[[2025,4,10]],"date-time":"2025-04-10T00:00:00Z","timestamp":1744243200000},"content-version":"unspecified","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-sa\/4.0"}],"content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2025,5]]},"abstract":"<jats:title>\n                    A\n                    <jats:sc>BSTRACT<\/jats:sc>\n                  <\/jats:title>\n                  <jats:p>Lymphangiomas are uncommon congenital hamartomas of the lymphatic system with a marked predilection for the head-and-neck region accounting for 75% of all cases. Lymphangiomas rarely affect the oral cavity. Affected sites in the oral cavity may include the tongue, palate, gingiva, lips, and alveolar ridge of the mandible. The anterior two-thirds on the dorsal surface of the tongue is the most common site for intraoral lymphangiomas leading to macroglossia, similar to the presentation in our case. Congenital macroglossia is a rare clinical condition characterized by an enlarged tongue. This enlargement can lead to a variety of oral and facial problems, with structural deformities such as diastema, disproportionate mandibular growth, and functional disorders such as difficulty in eating and swallowing, speech impairment, or even difficulty in breathing if it is severe. Macroglossia may be attributed to multiple underlying causes. These include conditions such as idiopathic muscular hypertrophy (notably in Beckwith\u2013Wiedemann syndrome), vascular malformations (such as angiomas and lymphangiomas), tumors, and endocrine disorders. Among these causes, lymphangiomatous macroglossia is particularly rare and is characterized by diffuse involvement. This type of macroglossia typically progresses chronically, reaching a developmental plateau at puberty without any spontaneous regression. We report a case of congenital macroglossia in an 8-year-old male due to lymphatic malformation and managed successfully.<\/jats:p>","DOI":"10.4103\/jiaps.jiaps_281_24","type":"journal-article","created":{"date-parts":[[2025,4,10]],"date-time":"2025-04-10T04:00:09Z","timestamp":1744257609000},"page":"403-406","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":2,"title":["Management of Congenital Macroglossia Due to Lymphatic Malformation in a Child with Review of Literature"],"prefix":"10.4103","volume":"30","author":[{"given":"Sushma","family":"Achugatla","sequence":"first","affiliation":[{"name":"Lilavati Hospital and Research Centre, Mumbai, Maharashtra, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Surendra","family":"Singh","sequence":"additional","affiliation":[{"name":"Lilavati Hospital and Research Centre, Mumbai, Maharashtra, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sonia","family":"Thakur","sequence":"additional","affiliation":[{"name":"Lilavati Hospital and Research Centre, Mumbai, Maharashtra, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Rajeev","family":"Redkar","sequence":"additional","affiliation":[{"name":"Lilavati Hospital and Research Centre, Mumbai, Maharashtra, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2025,4,10]]},"reference":[{"key":"R1-20250505","doi-asserted-by":"crossref","first-page":"489","DOI":"10.18203\/2319-2003.ijbcp20231133","article-title":"A case report on Beckwith-Wiedemann syndrome with macroglossia","volume":"12","author":"Joel","year":"2023","journal-title":"Int J Basic Clin Pharmacol"},{"key":"R2-20250505","doi-asserted-by":"crossref","first-page":"651","DOI":"10.1177\/000348940311200714","article-title":"Acute edema of the tongue: A life-threatening condition","volume":"112","author":"Gadban","year":"2003","journal-title":"Ann Otol Rhinol Laryngol"},{"key":"R3-20250505","doi-asserted-by":"crossref","first-page":"874","DOI":"10.1016\/j.ijom.2020.01.005","article-title":"Comprehensive treatment of massive macroglossia due to venous and lymphatic malformations","volume":"49","author":"Chen","year":"2020","journal-title":"Int J Oral Maxillofac Surg"},{"key":"R4-20250505","doi-asserted-by":"crossref","first-page":"1359","DOI":"10.1097\/SCS.0b013e3181ae42fa","article-title":"Course and distribution of the lingual nerve in the ventral tongue region anatomical considerations for frenectomy","volume":"20","author":"Yang","year":"2009","journal-title":"J Craniofac Surg"},{"key":"R5-20250505","doi-asserted-by":"crossref","first-page":"240","DOI":"10.1097\/SAP.0b013e3181f77a83","article-title":"Double stellate tongue reduction: A new method of treatment for macroglossia in patients with Beckwith-Wiedemann syndrome","volume":"67","author":"Hettinger","year":"2011","journal-title":"Ann Plast Surg"},{"key":"R6-20250505","doi-asserted-by":"crossref","first-page":"624","DOI":"10.1177\/000348940611500809","article-title":"Submucosal minimally invasive lingual excision: An effective, novel surgery for pediatric tongue base reduction","volume":"115","author":"Maturo","year":"2006","journal-title":"Ann Otol Rhinol Laryngol"}],"container-title":["Journal of Indian Association of Pediatric Surgeons"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.4103\/jiaps.jiaps_281_24","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T19:43:46Z","timestamp":1787773426000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.4103\/jiaps.jiaps_281_24"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,4,10]]},"references-count":6,"journal-issue":{"issue":"3","published-print":{"date-parts":[[2025]]}},"URL":"https:\/\/doi.org\/10.4103\/jiaps.jiaps_281_24","relation":{},"ISSN":["0971-9261","1998-3891"],"issn-type":[{"value":"0971-9261","type":"print"},{"value":"1998-3891","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,4,10]]},"assertion":[{"value":"2024-11-29","name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2025-01-19","name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}}]}}