{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T15:21:47Z","timestamp":1787757707728,"version":"build-2784847793"},"reference-count":9,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"4","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2021,10]]},"abstract":"<jats:sec>\n                    <jats:title\/>\n                    <jats:p>We report a case of a huge congenital pulmonary airway malformation (CPAM) that was referred as congenital diaphragmatic hernia (CDH). Initial ultrasound evaluation revealed a huge cystic lesion with septations, in the thorax, causing mediastinal shift and compression effects, suggesting the possibility of a thoracic lymphangioma, or bowel herniation with obstruction. A fetal magnetic resonance imaging reported possible bowel herniation through a posterior defect in the diaphragm, with volvulus, reinforcing the diagnosis of CDH. It was only on autopsy and subsequent histopathology examination that the diagnosis of a rare variant of CPAM\u2013nonmucinous papillary type, could be made. To the best of our knowledge, a CPAM this huge has not been reported prenatally at this gestation. We recommend considering the potential diagnosis of CPAM in any thoracic cystic irrespective of its size or appearance.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.4103\/jmu.jmu_139_20","type":"journal-article","created":{"date-parts":[[2021,12,17]],"date-time":"2021-12-17T01:12:07Z","timestamp":1639703527000},"page":"284-287","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Atypical Antenatal Presentation of an Unusual Nonmucinous Papillary Variant of Giant Congenital Pulmonary Airway Malformation Masquerading as Congenital Diaphragmatic Hernia with Volvulus"],"prefix":"10.4103","volume":"29","author":[{"given":"Basil","family":"Mathews","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Balaganesh","family":"Karmegaraj","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"C","family":"Vidya","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Vivek","family":"Krishnan","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","reference":[{"key":"R1-10-20240830","doi-asserted-by":"crossref","first-page":"101","DOI":"10.1159\/000440894","article-title":"Prenatal and postnatal management of congenital pulmonary airway malformation","volume":"110","author":"David","year":"2016","journal-title":"Neonatology"},{"key":"R2-10-20240830","doi-asserted-by":"crossref","first-page":"299","DOI":"10.12659\/PJR.901447","article-title":"An atypical presentation of congenital pulmonary airway malformation (CPAM): A Rare case with antenatal ultrasound findings and review of literature","volume":"82","author":"Gautam","year":"2017","journal-title":"Pol J Radiol"},{"key":"R4-10-20240830","doi-asserted-by":"crossref","first-page":"52","DOI":"10.1186\/s12890-020-1088-z","article-title":"case report of an unusual non-mucinous papillary variant of CPAM type 1 with KRAS mutations","volume":"20","author":"Koopman","year":"2020","journal-title":"BMC Pulm Med"},{"key":"R5-10-20240830","first-page":"200","article-title":"Congenital pulmonary airway malformation type 2: A case report with review of the literature","volume":"32","author":"Tastekin","year":"2016","journal-title":"Turk J Pathol"},{"key":"R7-10-20240830","first-page":"F372","article-title":"Diagnostic accuracy of imaging studies in congenital lung malformations","volume":"104","author":"Mon","year":"2019","journal-title":"Arch Dis Child-Fetal Neonatal Ed"},{"key":"R8-10-20240830","doi-asserted-by":"crossref","first-page":"1073","DOI":"10.1016\/j.athoracsur.2012.05.110","article-title":"Management of giant congenital pulmonary airway malformations requiring pneumonectomy","volume":"94","author":"Ben-Ishay","year":"2012","journal-title":"Ann Thorac Surg"},{"key":"R9-10-20240830","doi-asserted-by":"crossref","first-page":"331","DOI":"10.1053\/jpsu.2002.30832","article-title":"Cystic adenomatoid malformation volume ratio predicts outcome in prenatally diagnosed cystic adenomatoid malformation of the lung","volume":"37","author":"Crombleholme","year":"2002","journal-title":"J Pediatr Surg"},{"key":"R10-10-20240830","doi-asserted-by":"crossref","first-page":"618","DOI":"10.1016\/S0046-8177(99)90084-9","article-title":"Congenital cystic adenomatoid malformation of the lung (CCAM): Evaluation of the cellular components","volume":"30","author":"Morotti","year":"1999","journal-title":"Hum Pathol"},{"key":"R11-10-20240830","doi-asserted-by":"crossref","first-page":"14","DOI":"10.1002\/ppul.20917","article-title":"Pulmonary cysts in early childhood and the risk of malignancy","volume":"44","author":"Priest","year":"2009","journal-title":"Pediatr Pulmonol"}],"container-title":["Journal of Medical Ultrasound"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.4103\/JMU.JMU_139_20","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:48:25Z","timestamp":1787755705000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.4103\/JMU.JMU_139_20"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2021,10]]},"references-count":9,"journal-issue":{"issue":"4","published-print":{"date-parts":[[2021]]}},"URL":"https:\/\/doi.org\/10.4103\/jmu.jmu_139_20","relation":{},"ISSN":["0929-6441"],"issn-type":[{"value":"0929-6441","type":"print"}],"subject":[],"published":{"date-parts":[[2021,10]]}}}