{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,27]],"date-time":"2026-08-27T14:37:46Z","timestamp":1787841466741,"version":"build-2784847793"},"reference-count":10,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"4","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":["J West Afr Coll Surg"],"published-print":{"date-parts":[[2024,10]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:p>Popliteal pterygium syndrome (PPS) is a rare inherited disorder involving the face, limbs, and genitalia. The most prominent and handicapping deformity associated with this syndrome is Popliteal pterygium. Popliteal pterygium is a contracture band that extends from ischial tuberosity to calcaneum. It is a dense fibrous band difficult to correct surgically. We report a case of PPS with her two other family members diagnosed with Van der Woude syndrome. Single-stage surgical release is ineffective due to shortened neurovascular and surrounding soft tissues. Multimodality treatment with surgical release and motivated parents may help these children to rehabilitate.<\/jats:p>","DOI":"10.4103\/jwas.jwas_173_23","type":"journal-article","created":{"date-parts":[[2024,7,20]],"date-time":"2024-07-20T03:00:08Z","timestamp":1721444408000},"page":"445-449","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Popliteal Pterygium Syndrome with a Family History of Van der Woude Syndrome: A Case Report"],"prefix":"10.4103","volume":"14","author":[{"given":"Jiten Kumar","family":"Mishra","sequence":"first","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Shamendra Anand","family":"Sahu","sequence":"additional","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Aparajita","family":"Saha","sequence":"additional","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Abi","family":"Sindhuja","sequence":"additional","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jalaz Joezer","family":"Rahmi","sequence":"additional","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Abhijith","family":"Valsalan","sequence":"additional","affiliation":[{"name":"Department of Burns & Plastic Surgery, All India Institute of Medical Sciences, Raipur, Chhattisgarh, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2024,7,18]]},"reference":[{"key":"CIT0001-20240907","doi-asserted-by":"crossref","first-page":"333","DOI":"10.4103\/0970-4388.86382","article-title":"Popliteal pterygium syndrome: Orofacial and general features","volume":"29","author":"Bahetwar","year":"2011","journal-title":"J Indian Soc Pedod Prev Dent"},{"key":"CIT0002-20240907","doi-asserted-by":"crossref","first-page":"17","DOI":"10.1016\/0165-5876(88)90046-8","article-title":"Popliteal pterygium syndrome","volume":"15","author":"Deskin","year":"1988","journal-title":"Int J Pediatr Otorhinolaryngol"},{"key":"CIT0003-20240907","doi-asserted-by":"crossref","first-page":"503","DOI":"10.1542\/peds.41.2.503","article-title":"Popliteal pterygium syndrome. A syndrome comprising cleft lip-palate, popliteal and intercrural pterygia, digital and genital anomalies","volume":"41","author":"Gorlin","year":"1968","journal-title":"Pediatrics"},{"key":"CIT0004-20240907","doi-asserted-by":"crossref","first-page":"e3913","DOI":"10.1097\/GOX.0000000000003913","article-title":"Surgical correction of popliteal pterygium with serial splinting: A case report and review of literature","volume":"9","author":"Sewilam","year":"2021","journal-title":"Plast Reconstr Surg Glob Open"},{"key":"CIT0005-20240907","doi-asserted-by":"crossref","first-page":"471","DOI":"10.1186\/1752-1947-8-471","article-title":"Clinical and molecular findings in a Moroccan patient with popliteal pterygium syndrome: A case report","volume":"8","author":"Ratbi","year":"2014","journal-title":"J Med Case Reports"},{"key":"CIT0006-20240907","doi-asserted-by":"crossref","first-page":"285","DOI":"10.1038\/ng985","article-title":"Mutations in IRF6 cause Van der Woude and popliteal pterygium syndromes","volume":"32","author":"Kondo","year":"2002","journal-title":"Nat Genet"},{"key":"CIT0007-20240907","doi-asserted-by":"crossref","first-page":"927","DOI":"10.1016\/S0022-3476(67)80265-8","article-title":"Heritable dysmorphic syndrome with normal intelligence","volume":"70","author":"Hecht","year":"1967","journal-title":"J Pediatr"},{"key":"CIT0008-20240907","doi-asserted-by":"crossref","first-page":"355","DOI":"10.1302\/0301-620X.41B2.355","article-title":"Congenital popliteal webbing in siblings; a report of two cases","volume":"41-B","author":"Champion","year":"1959","journal-title":"J Bone Joint Surg Br"},{"key":"CIT0009-20240907","doi-asserted-by":"crossref","first-page":"339","DOI":"10.1097\/00006534-197509000-00020","article-title":"The surgical treatment of congenital webbing (pterygium) of the popliteal area","volume":"56","author":"Tuerk","year":"1975","journal-title":"Plast Reconstr Surg"},{"key":"CIT0010-20240907","doi-asserted-by":"crossref","first-page":"236","DOI":"10.4055\/cios.2009.1.4.236","article-title":"Treatment of popliteal pterygium using an Ilizarov external fixator","volume":"1","author":"Kim","year":"2009","journal-title":"Clin Orthop Surg"}],"container-title":["Journal of West African College of Surgeons"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.4103\/jwas.jwas_173_23","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,27]],"date-time":"2026-08-27T13:56:23Z","timestamp":1787838983000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.4103\/jwas.jwas_173_23"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2024,7,18]]},"references-count":10,"journal-issue":{"issue":"4","published-print":{"date-parts":[[2024]]}},"URL":"https:\/\/doi.org\/10.4103\/jwas.jwas_173_23","relation":{},"ISSN":["2276-6944","2992-5827"],"issn-type":[{"value":"2276-6944","type":"print"},{"value":"2992-5827","type":"electronic"}],"subject":[],"published":{"date-parts":[[2024,7,18]]},"assertion":[{"value":"2023-11-03","name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2023-12-26","name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}}]}}