{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:19:25Z","timestamp":1787750365830,"version":"build-2784847793"},"reference-count":10,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"2","license":[{"start":{"date-parts":[[2026,5,1]],"date-time":"2026-05-01T00:00:00Z","timestamp":1777593600000},"content-version":"unspecified","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0"}],"content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2026,5]]},"abstract":"<jats:title>Abstract:<\/jats:title>\n                  <jats:p>Wildervanck syndrome, also called as cervico-oculo-acoustic syndrome. This is characterized by the triad of Klippel\u2013Feil syndrome, Duane retraction syndrome, and congenital deafness. Other associations described are cardiovascular and musculoskeletal abnormalities. Some reports, in fact, state that nearly one percent of hearing-impaired females may be affected by Wildervanck syndrome. In our case report, a child who had the complete triad of the syndrome along with arachnodactyly (long slender digits), camptodactyly, short stature, and facial nerve paresis has been described.<\/jats:p>","DOI":"10.4103\/ojo.ojo_130_25","type":"journal-article","created":{"date-parts":[[2026,6,24]],"date-time":"2026-06-24T02:00:12Z","timestamp":1782266412000},"page":"259-262","update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["A unique case report of Wildervanck syndrome in association with facial nerve paresis and arachnodactyly"],"prefix":"10.4103","volume":"19","author":[{"given":"P.","family":"Surekha","sequence":"first","affiliation":[{"name":"Department of Pediatric Ophthalmology, Sankara Eye Hospital, Shimoga, Karnataka, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"V.","family":"Kavitha","sequence":"additional","affiliation":[{"name":"Department of Pediatric Ophthalmology, Sankara Eye Hospital, Shimoga, Karnataka, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Pravallika","family":"Penugonda","sequence":"additional","affiliation":[{"name":"Department of Pediatric Ophthalmology, Sankara Eye Hospital, Shimoga, Karnataka, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Mallikarjun M.","family":"Heralgi","sequence":"additional","affiliation":[{"name":"Department of Cornea Refractive Services, Sankara Eye Hospital, Shimoga, Karnataka, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2026,6,24]]},"reference":[{"key":"R2-20260624","doi-asserted-by":"crossref","first-page":"588","DOI":"10.1086\/514346","article-title":"Mendelian inheritance in man and its online version, OMIM","volume":"80","author":"McKusick","year":"2007","journal-title":"Am J Hum Genet"},{"key":"R4-20260624","doi-asserted-by":"crossref","first-page":"160","DOI":"10.1111\/j.1440-1673.1996.tb00373.x","article-title":"Wildervanck syndrome","volume":"40","author":"Kumar","year":"1996","journal-title":"Australas Radiol"},{"key":"R5-20260624","doi-asserted-by":"crossref","first-page":"72","DOI":"10.1136\/jmg.20.1.72","article-title":"Wildervanck's syndrome with bilateral subluxation of lens and facial paralysis","volume":"20","author":"Strisciuglio","year":"1983","journal-title":"J Med Genet"},{"key":"R6-20260624","first-page":"180","article-title":"Wildervanck syndrome (cervico-oculo-acoustic syndrome)","volume":"38","author":"Gupte","year":"1992","journal-title":"J Postgrad Med"},{"key":"R7-20260624","doi-asserted-by":"crossref","first-page":"301","DOI":"10.3928\/0191-3913-19990901-14","article-title":"Crocodile tears and dandy-walker syndrome in cervico-oculo-acoustic syndrome","volume":"36","author":"Haciyakupoglu","year":"1999","journal-title":"J Pediatr Ophthalmol Strabismus"},{"key":"R8-20260624","doi-asserted-by":"crossref","first-page":"323","DOI":"10.4103\/0301-4738.64120","article-title":"Wildervanck syndrome associated with cleft palate and short stature","volume":"58","author":"Kumar","year":"2010","journal-title":"Indian J Ophthalmol"},{"key":"R9-20260624","first-page":"e202202624","article-title":"Wildervanck syndrome: Clinical case report","volume":"121","author":"Chima-Gal\u00e1n","year":"2023","journal-title":"Arch Argent Pediatr"},{"key":"R10-20260624","first-page":"w03182","article-title":"Wildervanck Syndrome \u2013 a review of the \u201ctriad\u201dand its variations","volume":"172","author":"Bagaria","year":"2021","journal-title":"Swiss Arch Neurol Psychiatr Psychother"},{"key":"R11-20260624","doi-asserted-by":"crossref","first-page":"118","DOI":"10.2214\/ajr.97.1.118","article-title":"A simple screening test for the Marfan syndrome","volume":"97","author":"Steinberg","year":"1966","journal-title":"Am J Roentgenol Radium Ther Nucl Med"},{"key":"R12-20260624","doi-asserted-by":"crossref","first-page":"276","DOI":"10.1001\/archinte.1970.00310080082011","article-title":"The wrist sign. A useful physical finding in the Marfan syndrome","volume":"126","author":"Walker","year":"1970","journal-title":"Arch Intern Med"}],"container-title":["Oman Journal of Ophthalmology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.4103\/ojo.ojo_130_25","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T12:27:32Z","timestamp":1787747252000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.4103\/ojo.ojo_130_25"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,5]]},"references-count":10,"journal-issue":{"issue":"2","published-print":{"date-parts":[[2026]]}},"URL":"https:\/\/doi.org\/10.4103\/ojo.ojo_130_25","relation":{},"ISSN":["0974-620X","0974-7842"],"issn-type":[{"value":"0974-620X","type":"print"},{"value":"0974-7842","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,5]]},"assertion":[{"value":"2025-03-27","name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2026-02-20","name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}}]}}