{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,7,2]],"date-time":"2025-07-02T19:40:05Z","timestamp":1751485205732,"version":"3.41.0"},"reference-count":9,"publisher":"International College of Surgeons","issue":"4","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2011,10]]},"abstract":"<jats:title>Abstract<\/jats:title>\n        <jats:p>Choledochal cysts are common in Asian children. Primary sclerosing cholangitis (PSC), which is characterized by inflammation and fibrosis and may lead to bile duct stricture over the intrahepatic or extrahepatic bile duct, is rare in children. Here we report a case of a 10-year-old boy who presented with a choledochal cyst originating from PSC. He had suffered from repeated abdominal pain and cholangitis for 3\u00a0years. A type IV choledochal cyst was suspected from the ultrasound and computed tomography image showing a distended gallbladder and dilatation of the bilateral intrahepatic duct at the hepatic hilar area and common bile duct (CBD). During laparotomy, a markedly distended gallbladder was noted and was shown to have no communication with the CBD by intraoperative cholangiogram. Choledochal cysts with extrahepatic and intrahepatic duct dilatation at the hilar area and marked stenosis with nearly total obstruction of the distal CBD were noted. Hepaticojejunostomy was performed. The histopathologic findings demonstrated a typical PSC picture. The patient's postoperative course was uneventful for 8\u00a0months after surgery, and he received no medication during a regular follow-up.<\/jats:p>","DOI":"10.9738\/cc25.1","type":"journal-article","created":{"date-parts":[[2012,12,13]],"date-time":"2012-12-13T18:35:57Z","timestamp":1355423757000},"page":"316-319","source":"Crossref","is-referenced-by-count":2,"title":["Choledochal Cyst Originating from Primary Sclerosing Cholangitis in a Child"],"prefix":"10.9738","volume":"96","author":[{"given":"Wei-Lung","family":"Tseng","sequence":"first","affiliation":[{"name":"Department of Surgery, National Taiwan University Hospital and National Taiwan University College of Medicine, Taipei, Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hao-Yu","family":"Lin","sequence":"additional","affiliation":[{"name":"Department of Surgery, National Taiwan University Hospital and National Taiwan University College of Medicine, Taipei, Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Wen-Hsi","family":"Lin","sequence":"additional","affiliation":[{"name":"Department of Surgery, National Taiwan University Hospital and National Taiwan University College of Medicine, Taipei, Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hong-Shiee","family":"Lai","sequence":"additional","affiliation":[{"name":"Department of Surgery, National Taiwan University Hospital and National Taiwan University College of Medicine, Taipei, Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"4721","reference":[{"issue":"11","key":"i0020-8868-96-4-316-Iwai1","series-title":"Pediatr Surg Int","first-page":"995","article-title":"Choledochal cyst associated with duodenal atresia: case report and review of the literature.","volume":"25","author":"Iwai, A","year":"2009","unstructured":"Iwai, A, HamadaY, TakadaK, InagakiN, NakatakeR, YanaiH, et al. Choledochal cyst associated with duodenal atresia: case report and review of the literature.Pediatr Surg Int2009. 25 (11):995\u2013998."},{"issue":"4","key":"i0020-8868-96-4-316-Lee1","series-title":"Pediatr Surg Int","first-page":"355","article-title":"Laparoscopic excision of choledochal cysts in children: an intermediate-term report.","volume":"25","author":"Lee, KH","year":"2009","unstructured":"Lee, KH, TamYH, YeungCK, ChanKW, SihoeJD, CheungST, et al. Laparoscopic excision of choledochal cysts in children: an intermediate-term report.Pediatr Surg Int2009. 25 (4):355\u2013360."},{"issue":"3","key":"i0020-8868-96-4-316-LaRusso1","series-title":"Hepatology","first-page":"746","article-title":"Primary sclerosing cholangitis: summary of a workshop.","volume":"44","author":"LaRusso, NF","year":"2006","unstructured":"LaRusso, NF, ShneiderBL, BlackD, GoresGJ, JamesSP, DooE, et al. Primary sclerosing cholangitis: summary of a workshop.Hepatology2006. 44 (3):746\u2013764."},{"issue":"2","key":"i0020-8868-96-4-316-Chapman1","series-title":"Hepatology","first-page":"660","article-title":"Diagnosis and management of primary sclerosing cholangitis.","volume":"51","author":"Chapman, R","year":"2010","unstructured":"Chapman, R, FeveryJ, KallooA, NagorneyDM, BobergKM, ShneiderB, et al. Diagnosis and management of primary sclerosing cholangitis.Hepatology2010. 51 (2):660\u2013678."},{"issue":"10","key":"i0020-8868-96-4-316-Lindor1","series-title":"N Engl J Med","first-page":"691","article-title":"Ursodiol for primary sclerosing cholangitis. Mayo Primary Sclerosing Cholangitis-Ursodeoxycholic Acid Study Group.","volume":"336","author":"Lindor, KD","year":"1997","unstructured":"Lindor, KD\n          . Ursodiol for primary sclerosing cholangitis. Mayo Primary Sclerosing Cholangitis-Ursodeoxycholic Acid Study Group.N Engl J Med1997. 336 (10):691\u2013695."},{"issue":"3","key":"i0020-8868-96-4-316-Kerkar1","series-title":"Curr Gastroenterol Rep","first-page":"195","article-title":"Sclerosing cholangitis: pediatric perspective.","volume":"12","author":"Kerkar, N","year":"2010","unstructured":"Kerkar, N and MilohT. Sclerosing cholangitis: pediatric perspective.Curr Gastroenterol Rep2010. 12 (3):195\u2013202."},{"issue":"1","key":"i0020-8868-96-4-316-Tyson1","series-title":"Hepatology","first-page":"173","article-title":"Risk factors of cholangiocarcinoma.","volume":"54","author":"Tyson, GL","year":"2011","unstructured":"Tyson, GL and El-SeragHB. Risk factors of cholangiocarcinoma.Hepatology2011. 54 (1):173\u2013184."},{"issue":"3","key":"i0020-8868-96-4-316-Lindor2","series-title":"Hepatology","first-page":"808","article-title":"High-dose ursodeoxycholic acid for the treatment of primary sclerosing cholangitis.","volume":"50","author":"Lindor, KD","year":"2009","unstructured":"Lindor, KD, KowdleyKV, LuketicVA, HarrisonME, McCashlandT, BefelerAS, et al. High-dose ursodeoxycholic acid for the treatment of primary sclerosing cholangitis.Hepatology2009. 50 (3):808\u2013814."},{"issue":"2","key":"i0020-8868-96-4-316-Miloh1","series-title":"Clin Gastroenterol Hepatol","first-page":"239","article-title":"A retrospective single-center review of primary sclerosing cholangitis in children.","volume":"7","author":"Miloh, T","year":"2009","unstructured":"Miloh, T, ArnonR, ShneiderB, SuchyF, and KerkarN. A retrospective single-center review of primary sclerosing cholangitis in children.Clin Gastroenterol Hepatol2009. 7 (2):239\u2013245."}],"container-title":["International Surgery"],"original-title":[],"link":[{"URL":"https:\/\/international-surgery.kglmeridian.com\/view\/journals\/insu\/96\/4\/article-p316.xml","content-type":"text\/html","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/meridian.allenpress.com\/international-surgery\/article-pdf\/96\/4\/316\/2213757\/cc25_1.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/international-surgery.kglmeridian.com\/downloadpdf\/journals\/insu\/96\/4\/article-p316.xml","content-type":"text\/html","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/international-surgery.kglmeridian.com\/downloadpdf\/journals\/insu\/96\/4\/article-p316.xml","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2025,7,2]],"date-time":"2025-07-02T19:06:24Z","timestamp":1751483184000},"score":1,"resource":{"primary":{"URL":"https:\/\/international-surgery.kglmeridian.com\/view\/journals\/insu\/96\/4\/article-p316.xml"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2011,10]]},"references-count":9,"journal-issue":{"issue":"4"},"URL":"https:\/\/doi.org\/10.9738\/cc25.1","relation":{},"ISSN":["0020-8868","2520-2456"],"issn-type":[{"type":"print","value":"0020-8868"},{"type":"electronic","value":"2520-2456"}],"subject":[],"published":{"date-parts":[[2011,10]]}}}